Novel mutations in the ZEB1 gene identified in Czech and British patients with posterior polymorphous corneal dystrophy

Hum Mutat. 2007 Jun;28(6):638. doi: 10.1002/humu.9495.

Abstract

We describe the search for mutations in six unrelated Czech and four unrelated British families with posterior polymorphous corneal dystrophy (PPCD); a relatively rare eye disorder. Coding exons and intron/exon boundaries of all three genes (VSX1, COL8A2, and ZEB1/TCF8) previously reported to be implicated in the pathogenesis of this disorder were screened by DNA sequencing. Four novel pathogenic mutations were identified in four families; two deletions, one nonsense, and one duplication within exon 7 in the ZEB1 gene located at 10p11.2. We also genotyped the Czech patients to test for a founder haplotype and lack of disease segregation with the 20p11.2 locus we previously described. Although a systematic clinical examination was not performed, our investigation does not support an association between ZEB1 changes and self reported non-ocular anomalies. In the remaining six families no disease causing mutations were identified thereby indicating that as yet unidentified gene(s) are likely to be responsible for PPCD.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Collagen Type VIII / genetics
  • Corneal Dystrophies, Hereditary / genetics*
  • Czech Republic
  • DNA Mutational Analysis
  • Eye Proteins / genetics
  • Female
  • Homeodomain Proteins / genetics*
  • Humans
  • Male
  • Middle Aged
  • Mutation*
  • Pedigree
  • Rare Diseases / genetics
  • Transcription Factors / genetics*
  • United Kingdom
  • Zinc Finger E-box-Binding Homeobox 1

Substances

  • COL8A2 protein, human
  • Collagen Type VIII
  • Eye Proteins
  • Homeodomain Proteins
  • Transcription Factors
  • VSX1 protein, human
  • ZEB1 protein, human
  • Zinc Finger E-box-Binding Homeobox 1