A Brazilian registry of juvenile dermatomyositis: onset features and classification of 189 cases

Clin Exp Rheumatol. 2009 Nov-Dec;27(6):1031-8.

Abstract

Objective: To describe onset features, classification and treatment of juvenile dermatomyositis (JDM) and juvenile polymyositis (JPM) from a multicentre registry.

Methods: Inclusion criteria were onset age lower than 18 years and a diagnosis of any idiopathic inflammatory myopathy (IIM) by attending physician. Bohan & Peter (1975) criteria categorisation was established by a scoring algorithm to define JDM and JPM based on clinical protocol data.

Results: Of the 189 cases included, 178 were classified as JDM, 9 as JPM (19.8: 1) and 2 did not fit the criteria; 6.9% had features of chronic arthritis and connective tissue disease overlap. Diagnosis classification agreement occurred in 66.1%. Median onset age was 7 years, median follow-up duration was 3.6 years. Malignancy was described in 2 (1.1%) cases. Muscle weakness occurred in 95.8%; heliotrope rash 83.5%; Gottron plaques 83.1%; 92% had at least one abnormal muscle enzyme result. Muscle biopsy performed in 74.6% was abnormal in 91.5% and electromyogram performed in 39.2% resulted abnormal in 93.2%. Logistic regression analysis was done in 66 cases with all parameters assessed and only aldolase resulted significant, as independent variable for definite JDM (OR=5.4, 95%CI 1.2-24.4, p=0.03). Regarding treatment, 97.9% received steroids; 72% had in addition at least one: methotrexate (75.7%), hydroxychloroquine (64.7%), cyclosporine A (20.6%), IV immunoglobulin (20.6%), azathioprine (10.3%) or cyclophosphamide (9.6%). In this series 24.3% developed calcinosis and mortality rate was 4.2%.

Conclusion: Evaluation of predefined criteria set for a valid diagnosis indicated aldolase as the most important parameter associated with definite JDM category. In practice, prednisone-methotrexate combination was the most indicated treatment.

Publication types

  • Multicenter Study

MeSH terms

  • Adolescent
  • Age of Onset
  • Brazil
  • Child
  • Child, Preschool
  • Dermatomyositis / classification*
  • Dermatomyositis / diagnosis*
  • Dermatomyositis / drug therapy
  • Disease Progression
  • Female
  • Glucocorticoids / therapeutic use
  • Humans
  • Infant
  • Male
  • Patient Selection
  • Registries
  • Regression Analysis
  • Severity of Illness Index
  • Treatment Outcome

Substances

  • Glucocorticoids