Glutathione S-transferase P1 single nucleotide polymorphism predicts permanent ototoxicity in children with medulloblastoma

Pediatr Blood Cancer. 2013 Apr;60(4):593-8. doi: 10.1002/pbc.24366. Epub 2012 Oct 12.

Abstract

Background: Glutathione S-transferase (GST) enzymes are involved in detoxifying chemotherapy and clearing reactive oxygen species formed by radiation. We explored the relationship between the host GSTP1 105 A > G polymorphism (rs1695), tumor GSTpi protein expression, and clinical outcomes in pediatric medulloblastoma. We hypothesized that the GSTP1 105 G-allele and increased tumor GSTpi expression would be associated with lower progression-free survival and fewer adverse events.

Procedure: The study included 106 medulloblastoma/primitive neuroectodermal tumor (PNET) patients seen at Texas Children's Cancer Center. Genotyping was performed using an Illumina HumanOmni1-Quad BeadChip and GSTpi expression was assessed using immunohistochemistry. We used the Kaplan-Meier method for survival analyses and logistic regression for toxicity comparisons.

Results: Patients with a GSTP1 105 AG/GG genotype (vs. AA) or who had received high dose craniospinal radiation (≥34 Gy vs. <26 Gy) had a greater risk of requiring hearing aids than their counterparts (OR 4.0, 95% CI 1.2-13.6, and OR 3.1, 95% CI 1.1-8.8, respectively, n = 69). Additionally, there was a statistically significant interaction between these variables. Compared with the lowest risk group (GSTP1 105 AA-low dose radiation), patients with a GSTP1 105 AG/GG genotype who received high dose radiation were 8.4 times more likely to require hearing aids (95% CI 1.4-49.9, p-trend = 0.005, n = 69). When adjusted for age, cumulative cisplatin dose, and amifostine use, the association remained.

Conclusions: The GSTP1 105 G-allele is associated with permanent ototoxicity in pediatric medulloblastoma/PNET and strongly interacts with radiation dose. Patients with this allele should be considered for clinical trials employing radiation dose modifications and cytoprotectant strategies.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Cerebellar Neoplasms / genetics
  • Cerebellar Neoplasms / mortality
  • Cerebellar Neoplasms / radiotherapy*
  • Child
  • Child, Preschool
  • Disease-Free Survival
  • Female
  • Genetic Predisposition to Disease / genetics*
  • Genotype
  • Glutathione S-Transferase pi / genetics*
  • Hearing Loss / etiology*
  • Humans
  • Immunohistochemistry
  • Infant
  • Kaplan-Meier Estimate
  • Male
  • Medulloblastoma / genetics
  • Medulloblastoma / mortality
  • Medulloblastoma / radiotherapy*
  • Neuroectodermal Tumors, Primitive / genetics
  • Neuroectodermal Tumors, Primitive / mortality
  • Neuroectodermal Tumors, Primitive / radiotherapy
  • Polymorphism, Single Nucleotide*
  • Radiotherapy / adverse effects*

Substances

  • GSTP1 protein, human
  • Glutathione S-Transferase pi