Impact of enzyme replacement therapy on linear growth in Korean patients with mucopolysaccharidosis type II (Hunter syndrome)

J Korean Med Sci. 2014 Feb;29(2):254-60. doi: 10.3346/jkms.2014.29.2.254. Epub 2014 Jan 28.

Abstract

Hunter syndrome (or mucopolysaccharidosis type II [MPS II]) arises because of a deficiency in the lysosomal enzyme iduronate-2-sulfatase. Short stature is a prominent and consistent feature in MPS II. Enzyme replacement therapy (ERT) with idursulfase (Elaprase®) or idursulfase beta (Hunterase®) have been developed for these patients. The effect of ERT on the growth of Korean patients with Hunter syndrome was evaluated at a single center. This study comprised 32 patients, who had received ERT for at least 2 yr; they were divided into three groups according to their ages at the start of ERT: group 1 (<6 yr, n=14), group 2 (6-10 yr, n=11), and group 3 (10-20 yr, n=7). The patients showed marked growth retardation as they got older. ERT may have less effect on the growth of patients with the severe form of Hunter syndrome. The height z-scores in groups 2 and 3 revealed a significant change (the estimated slopes before and after the treatment were -0.047 and -0.007, respectively: difference in the slope, 0.04; P<0.001). Growth in response to ERT could be an important treatment outcome or an endpoint for future studies.

Keywords: Elaprase; Enzyme Replacement Therapy; Growth; Hunter Syndrome; Hunterase; Mucopolysaccharidosis II.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Body Height
  • Child
  • Child, Preschool
  • Cognitive Dysfunction / etiology
  • Demography
  • Enzyme Replacement Therapy
  • Humans
  • Iduronate Sulfatase / therapeutic use*
  • Infant
  • Male
  • Mucopolysaccharidosis II / complications
  • Mucopolysaccharidosis II / diagnosis
  • Mucopolysaccharidosis II / therapy*
  • Mutation
  • Phenotype
  • Protein Isoforms / therapeutic use
  • Republic of Korea
  • Young Adult

Substances

  • Protein Isoforms
  • Iduronate Sulfatase
  • idursulfase