Efficacy of Rituximab in Refractory Generalized anti-AChR Myasthenia Gravis

J Neuromuscul Dis. 2018;5(2):241-249. doi: 10.3233/JND-180300.

Abstract

Background: Several retrospective case series have suggested rituximab (RTX) might improve patients with refractory Myasthenia Gravis (MG).

Objective: In this study, we aimed to evaluate prospectively the efficacy of RTX on muscle function in refractory generalized anti-acetylcholine receptor (AChR) MG patients.

Methods: Enrolled patients received 1 g of RTX at day 0, day 14, and 6-month follow-up (M6). The primary endpoint was improvement of muscle function at 12-month (M12) based on myasthenic muscle score (MMS). Secondary endpoints were an improvement of the MG Foundation of America Postintervention Status (MGFA-PIS), respiratory forced vital capacity, occurrences of acute MG exacerbation and requirement of associated immunosuppressants and immunomodulatory agents.

Results: Twelve patients were enrolled, and 11 completed the study. Only a single patient presented an improvement of at least 20 points on MMS at M12, although 2 patients displayed an increase of at least 18 points at M12. MGFA-PIS had improved in 55% of patients by M12. The clinical improvement was not associated with a reduction of immunosuppressant burden.

Conclusions: These results provide data on the effect of RTX in patients with severe, refractory anti-AChR Abs generalized MG. Even though primary outcome was only reached in a single patient at M12, a beneficial effect of RTX on muscle function was seen in half of the patients at M12 and persisted in a third of patients at M18.

Keywords: Myasthenia gravis; anti-AchR; anti-CD20 monoclonal antibodies; anti-acetylcholine receptor antibodies; refractory generalized myasthenia; rituximab.

Publication types

  • Clinical Trial, Phase II
  • Multicenter Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Autoantibodies / immunology
  • Female
  • Health Status
  • Humans
  • Immunologic Factors / therapeutic use*
  • Male
  • Middle Aged
  • Muscle Weakness / physiopathology
  • Myasthenia Gravis / drug therapy*
  • Myasthenia Gravis / immunology
  • Myasthenia Gravis / physiopathology
  • Pilot Projects
  • Quality of Life
  • Receptors, Cholinergic / immunology
  • Respiratory Function Tests
  • Rituximab / therapeutic use*
  • Treatment Outcome
  • Young Adult

Substances

  • Autoantibodies
  • Immunologic Factors
  • Receptors, Cholinergic
  • Rituximab