l-Serine Reduces Spinal Cord Pathology in a Vervet Model of Preclinical ALS/MND

J Neuropathol Exp Neurol. 2020 Apr 1;79(4):393-406. doi: 10.1093/jnen/nlaa002.

Abstract

The early neuropathological features of amyotrophic lateral sclerosis/motor neuron disease (ALS/MND) are protein aggregates in motor neurons and microglial activation. Similar pathology characterizes Guamanian ALS/Parkinsonism dementia complex, which may be triggered by the cyanotoxin β-N-methylamino-l-alanine (BMAA). We report here the occurrence of ALS/MND-type pathological changes in vervets (Chlorocebus sabaeus; n = 8) fed oral doses of a dry powder of BMAA HCl salt (210 mg/kg/day) for 140 days. Spinal cords and brains from toxin-exposed vervets were compared to controls fed rice flour (210 mg/kg/day) and to vervets coadministered equal amounts of BMAA and l-serine (210 mg/kg/day). Immunohistochemistry and quantitative image analysis were used to examine markers of ALS/MND and glial activation. UHPLC-MS/MS was used to confirm BMAA exposures in dosed vervets. Motor neuron degeneration was demonstrated in BMAA-dosed vervets by TDP-43+ proteinopathy in anterior horn cells, by reactive astrogliosis, by activated microglia, and by damage to myelinated axons in the lateral corticospinal tracts. Vervets dosed with BMAA + l-serine displayed reduced neuropathological changes. This study demonstrates that chronic dietary exposure to BMAA causes ALS/MND-type pathological changes in the vervet and coadministration of l-serine reduces the amount of reactive gliosis and the number of protein inclusions in motor neurons.

Keywords: ALS/MND; BMAA; Cyanobacteria; Guam ALS/PDC; Motor neurons; Neurofibrillary tangles; TDP-43.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Amino Acids, Diamino / toxicity
  • Amyotrophic Lateral Sclerosis / chemically induced
  • Amyotrophic Lateral Sclerosis / pathology*
  • Animals
  • Chlorocebus aethiops
  • Cyanobacteria Toxins
  • Disease Models, Animal
  • Male
  • Microglia / drug effects
  • Microglia / pathology
  • Motor Neuron Disease / chemically induced
  • Motor Neuron Disease / pathology*
  • Motor Neurons / drug effects*
  • Motor Neurons / pathology*
  • Pyramidal Tracts / drug effects
  • Pyramidal Tracts / pathology
  • Serine / administration & dosage*
  • Spinal Cord / drug effects*
  • Spinal Cord / pathology*

Substances

  • Amino Acids, Diamino
  • Cyanobacteria Toxins
  • beta-N-methylamino-L-alanine
  • Serine