Hypertension associated with fibromuscular dysplasia of renal artery is the most common form of secondary hypertension among young patients. In this article we present a case of a 27-year-old patient, with drug-resistant hypertension. Stenosis of right renal artery and small right kidney were found on ultrasonography, angio-CT and angiography. There was no sign of renal atrophy therefore we performed percutaneous transluminal angioplasty. After the procedure we observed a decrease in blood pressure and no need to use hypertensive medication. Diagnosis and treatment of this condition are discussed.